A case of Japanese Laing type distal myopathy with a mutation in <i>MYH7</i> gene

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Laing distal myopathy pathologically resembling inclusion body myositis

Mutations in MYH7 cause autosomal dominant Laing distal myopathy. We present a family with a previously reported deletion (c.5186_5188delAGA, p.K1729del). Muscle pathology in one family member was characterized by an inflammatory myopathy with rimmed vacuoles, increased MHC Class I expression, and perivascular and endomysial muscle inflammation comprising CD3(+), CD4(+), CD8(+), and CD68(+) inf...

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ژورنال

عنوان ژورنال: Rinsho Shinkeigaku

سال: 2019

ISSN: 0009-918X,1882-0654

DOI: 10.5692/clinicalneurol.cn-001333